CCDC28B

coiled-coil domain containing 28B

Ensembl:
ENSG00000160050
UniProt:
Q9BUN5
OMIM:
610162
Synonyms:
MGC1203, RP4-622L5.5

Cilia effects upon perturbation of CCDC28B

Cilia number / % ciliated:
Decreased cilia number
Loss-of-function effect:
Shorter cilia
Overexpression effect:
Longer cilia

Ciliogenesis screen results (2 screens)

  • Wheway et al. 2015 (siRNA) [siRNA]: No effect PMID:26167766
  • Breslow et al. 2018 (CRISPR) [CRISPR]: No Significant Effect PMID:29459680

Phenotypes

Mouse phenotype:
abnormal reti outer nuclear layer morphology, abnormal reti inner nuclear layer morphology

Ciliopathy associations

  • Bardet-Biedl Syndrome

Subcellular localization

basal body, centrosome

Functional category

  • Ciliary assembly/disassembly
  • Cilia length regulation

Function

Reportes as second site modifier of the ciliopathy Bardet-Biedl syndrome. It is a positive regulator of mTOR complex 2 and interacts with SIN1 and Kinesine 1 to regulate cilia length in vivo (23727834, 29445114).Transfected hTERT-RPE cells with our RNA oligos and measured the percentage of ciliated cells and the average ciliary length in controls, CCDC28B and IFT88 knockdown cells. We observed a significant reduction in both the number and length of cilia upon knockdown of CCDC28B(PMID: 23015189). CCDC28B maintains normal cilia length and ciliogenesis, LoF shortens cilia and reduces proportion of cilia-positive cells, OE can rescue(PMID: 29445114).

Model organism evidence

Mus musculus (2 references)

The present study investigates the role of CCDC28A, a protein expressed specifically in male germ cells, whose paralog CCDC28B has been implicated in ciliogenesis.

CCDC28B (coiled-coil domain-containing protein 28B) was identified as a modifier in the ciliopathy Bardet-Biedl syndrome (BBS).

PMIDs: 39500989, 35653384

Danio rerio (3 references)

CCDC28B (coiled-coil domain-containing protein 28B) was identified as a modifier in the ciliopathy Bardet-Biedl syndrome (BBS).

Kinesin 1 regulates cilia length through an interaction with the Bardet-Biedl syndrome related protein CCDC28B.

PMIDs: 35653384, 29445114, 23015189