DISC1

DISC1 scaffold protein

Ensembl:
ENSG00000162946
UniProt:
Q9NRI5
OMIM:
605210

Cilia effects upon perturbation of DISC1

Cilia number / % ciliated:
Decreased cilia number

Ciliogenesis screen results (3 screens)

  • Wheway et al. 2015 (siRNA) [siRNA]: Ciliogenesis Defect (z=-4.42) PMID:26167766
  • Breslow et al. 2018 (CRISPR) [CRISPR]: No Significant Effect PMID:29459680
  • Roosing et al. 2015 (siRNA) [siRNA]: No effect PMID:26595381

Phenotypes

Mouse phenotype:
abnormal spleen morphology, hyperactivity, increased prepulse inhibition
Mouse ciliopathy phenotype:
abnormal kidney morphology, cataract, enlarged heart, small kidney, abnormal heart morphology, abnormal vitreous body morphology

Subcellular localization

basal body, centrosome, cilia, transition zone

Functional category

  • Ciliary assembly/disassembly
  • Actin & cytoskeleton regulation
  • Neurogenesis & migration
  • Protein processing & maturation
  • Cell migration & adhesion
  • Signaling (Hedgehog, GPCRs, ion channels)
  • Transition zone

Function

Regulation of the formation and/or mainte nce of primary cilia, and establish subtype-specific targeting of dopamine receptors to the ciliary surface. Interacts with centriolar and ciliary components (20531939). Ciliogenesis and intraflagellar transport regulation through MIPT3 interaction. DISC1 is involved in plus-end and minus-end microtubular transport (28125008). DISC1 knockdown reduced the numbers of primary cilia.

Model organism evidence

Mus musculus (1 reference)

Mutations in Traf3ip1 reveal defects in ciliogenesis, embryonic development, and altered cell size regulation.

PMIDs: 21945076

Danio rerio (2 references)

Mutations in Traf3ip1 reveal defects in ciliogenesis, embryonic development, and altered cell size regulation.

An essential role for DYF-11/MIP-T3 in assembling functional intraflagellar transport complexes.

PMIDs: 21945076, 18369462

C. elegans (2 references)

Mutations in Traf3ip1 reveal defects in ciliogenesis, embryonic development, and altered cell size regulation.

An essential role for DYF-11/MIP-T3 in assembling functional intraflagellar transport complexes.

PMIDs: 21945076, 18369462