GID8

GID complex subunit 8 homolog

Ensembl:
ENSG00000101193
UniProt:
Q9NWU2
OMIM:
611625
Synonyms:
BA305P22.1, C20ORF11, FLJ20602, TWA1

Cilia effects upon perturbation of GID8

Ciliogenesis screen results (2 screens)

  • Breslow et al. 2018 (CRISPR) [CRISPR]: No Significant Effect PMID:29459680
  • Pusapati et al. 2018 (CRISPR) [CRISPR]: Negative Regulator (Hh signaling, pos_rank=119, lfc=0.98) PMID:30270045

Phenotypes

Mouse phenotype:
no spontaneous movement, preweaning lethality, complete penetrance

Subcellular localization

basal body, cilia

Functional category

  • Ciliary assembly/disassembly

Function

RMND5A and TWA1 are present at the basal body, at the axoneme in primary cilia and motile mono-cilia, and at the centrioles in cycling cells, and other integral components of the GID complex(ARMC8 and MKLN1) are present at the axoneme in primary cilia, suggesting that the GID complex has a function at the primary cilium(35543155).