LMX1B
LIM homeobox transcription factor 1 beta
- Ensembl:
- ENSG00000136944
- UniProt:
- O60663
- OMIM:
- 602575
- Synonyms:
- NPS1
Cilia effects upon perturbation of LMX1B
Ciliogenesis screen results (6 screens)
- Kim2016: Not Reported
- Wheway et al. 2015 (siRNA) [siRNA]: Ciliogenesis Defect (z=-7.98) PMID:26167766
- Breslow et al. 2018 (CRISPR) [CRISPR]: No Significant Effect PMID:29459680
- Basu et al. 2023 (siRNA) [siRNA]: Left-Right Asymmetry Candidate (Z2MCilia=-0.35) PMID:37771269
- Roosing et al. 2015 (siRNA) [siRNA]: Hyper-ciliogenesis (robust z=2.26, ciliated=54.9%) PMID:26595381
- Kim et al. 2010 (siRNA) [siRNA]: Longer Cilia (Area per Cilia z=3.63) PMID:20393562
Phenotypes
- Human ciliopathy phenotype:
- nail-patella-like renal disease
Subcellular localization
nucleoplasm
Function
Mutations in LMX1B cause Lowe Oculocerebrorenal Syndrome (PMID: 34195159).