MOSMO

modulator of smoothened

Ensembl:
ENSG00000185716
UniProt:
Q8NHV5
Synonyms:
ATTHOG, BC030336, C16ORF52

Cilia effects upon perturbation of MOSMO

Cilia number / % ciliated:
Unknown
Loss-of-function effect:
Unknown
Overexpression effect:
Unknown

Ciliopathy associations

  • Nonsyndromic Tetralogy of Fallot

Subcellular localization

cilia

Function

At the cellular level, Mosmoa localizes at the plasma membrane, cytoplasmic vesicles and primary cilium in both zebrafish and chick embryos. CRISPR/Cas9 mediated inactivation of both mosmoa and mosmob in zebrafish causes frontonasal hypoplasia and craniofacial skeleton defects, which become evident in the adult fish. We thus suggest that MOSMO is a candidate to explain uncharacterized forms of human congenital craniofacial malformations, such as those present in the 16p12.1 chromosomal deletion syndrome encompassing the MOSMO locus (PMID: 34746155).