RAB3GAP2
RAB3 GTPase activating non-catalytic protein subunit 2
- Ensembl:
- ENSG00000118873
- UniProt:
- Q9H2M9
- OMIM:
- 609275
- Synonyms:
- DKFZP434D245, KIAA0839, RAB3-GAP150, SPG69
Cilia effects upon perturbation of RAB3GAP2
Ciliogenesis screen results (1 screen)
- Breslow et al. 2018 (CRISPR) [CRISPR]: No Significant Effect PMID:29459680
Phenotypes
- Mouse phenotype:
- increased circulating alkaline phosphatase level; hyperactivity; abnormal optic disk morphology; decreased circulating HDL cholesterol level; prolonged RR interval; thrombocytopenia; decreased heart rate; decreased hematocrit; abnormal snout morphology; narrow eye opening
- Mouse ciliopathy phenotype:
- increased circulating bilirubin level; persistence of hyaloid vascular system; cataract
- Human ciliopathy phenotype:
- Cataract - intellectual disability - hypogonadism
Ciliopathy associations
- Warburg Micro Syndrome
Subcellular localization
cytosol, plasma membrane
Functional category
- Trafficking (BBSome, small GTPases, vesicular transport, ATPases)
Function
Mutations in RAB3GAP2 cause Warburg micro syndrome (PMID: 26063829).