ROPN1L

rhophilin associated tail protein 1 like

Ensembl:
ENSG00000145491
UniProt:
Q96C74
OMIM:
611756
Synonyms:
ASP, FLJ25776, LINC01513, RP11-1C1.7, RSPH11

Cilia effects upon perturbation of ROPN1L

Ciliogenesis screen results (2 screens)

  • Wheway et al. 2015 (siRNA) [siRNA]: Ciliogenesis Defect (z=-2.51) PMID:26167766
  • Breslow et al. 2018 (CRISPR) [CRISPR]: No Significant Effect PMID:29459680

Phenotypes

Mouse phenotype:
decreased grip strength, abnormal snout morphology, abnormal tooth morphology
Mouse ciliopathy phenotype:
kyphosis, abnormal spine curvature

Ciliopathy associations

  • Male Infertility

Subcellular localization

cilia

Functional category

  • Ciliary assembly/disassembly
  • Actin & cytoskeleton regulation
  • T cell biology
  • Reproduction & sperm
  • Protein processing & maturation
  • Cell migration & adhesion

Function

Functions as a key molecule in the mainte nce of basal ciliary beat frequency. Its role in ciliary motility coulb be played via regulation of axonemal sig ling (22021175)

Model organism evidence

Mus musculus (2 references)

Loss of NSUN7 altered the abundance of proteins essential for dynein arm assembly (PIH1D3, CCDC103, CCDC40), intraflagellar transport (IFT122), and fibrous sheath organization (AKAP3, AKAP4, ROPN1L).

The fibrous sheath (FS) is a flagellar cytoskeletal structure unique to sperm that surrounds the outer dense fibers and axoneme.

PMIDs: 41516134, 23303679