WWP1

WW domain containing E3 ubiquitin protein ligase 1

Ensembl:
ENSG00000123124
UniProt:
Q9H0M0
OMIM:
602307
Synonyms:
AIP5, DKFZP434D2111

Cilia effects upon perturbation of WWP1

Cilia number / % ciliated:
No effect
Loss-of-function effect:
No effect

Ciliogenesis screen results (4 screens)

  • Wheway et al. 2015 (siRNA) [siRNA]: Ciliogenesis Defect (z=-6.90) PMID:26167766
  • Breslow et al. 2018 (CRISPR) [CRISPR]: No Significant Effect PMID:29459680
  • Roosing et al. 2015 (siRNA) [siRNA]: No effect PMID:26595381
  • Pusapati et al. 2018 (CRISPR) [CRISPR]: Negative Regulator (Hh signaling, pos_rank=450, lfc=0.57) PMID:30270045

Phenotypes

Mouse phenotype:
decreased locomotor activity, decreased fasting circulating glucose level, increased circulating phosphate level
Mouse ciliopathy phenotype:
short tibia

Subcellular localization

cilia, cytosol, nucleus

Functional category

  • Ciliary assembly/disassembly
  • T cell biology
  • Viral interactions
  • Signaling (Hedgehog, GPCRs, ion channels)
  • Transcription regulation

Function

The ciliary E3, Wwp1, binds Ptch1 and localizes to cilia at the basal state. Activation of sig ling removes both Ptch1 and Wwp1 from cilia, thus providing an elegant mechanism for Ptch1 to regulate ciliary Smo levels(34161574).